Atypical retinitis pigmentosa associated with EYS variants

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Authors: Normila Barthelemy, Spencer C. Barrett, Winston Lee, Jesse D. Sengillo
Cited by: 1
References: 17

Abstract

Purpose To report an atypical phenotype of autosomal recessive retinitis pigmentosa (RP) associated with variants in the Eyes Shut Homolog ( EYS ) gene. Methods Case report Results A 53-year-old woman with a prior history of HIV controlled on HAART therapy presented with complaints of long-standing decreased vision and nyctalopia in both eyes. Visual acuity was light perception (LP) and 20/40 in the right and left eye, respectively. Examination disclosed an unremarkable anterior segment of both eyes. Dilated fundus exam revealed clear vitreous media, optic nerve pallor, vascular attenuation, peripheral retinal atrophy, old laser scars, and rare pigment migration bilaterally. In the right eye there was an evident tractional membrane along both arcades and significant subretinal exudation. OCT imaging showed chorioretinal atrophy in both eyes, and significant vitreoretinal traction in the right eye. A hyperautofluorescent ring was noted on fundus autofluorescence (FAF) of the left eye. An inherited retinal dystrophy was suspected, prompting genetic testing to be performed. Panel based testing revealed multiple EYS variants, namely c.2470T > C, c.3250A > C, c.4402G > C, and c.3443+1G > T. Conclusion Phenotypic heterogeneity of EYS -associated RP can lead to a delay in diagnosis for atypical cases. A prior coats-like response may be considered in asymmetric cases exhibiting significant exudation or tractional bands.

Fields of Study & Subjects

Ocular Diseases and Behçet’s Syndrome Retinal Development and Disorders Ocular Oncology and Treatments

Publication details

Journal / source
American Journal of Ophthalmology Case Reports
Publisher
Elsevier BV
Volume
42
Pages
102580–102580
Publication date
7 April 2026
Language
EN