Virus-associated immune dysregulation presenting as facial granulomatous dermatitis in DiGeorge syndrome: A case series

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Authors: Jinxiang Yang, Zhen Zhang, Guofang Li, Kexin Yan, Yali Song, Jiayan Zhang, Qiuyang Guo, Siyuan Zha, Peiyi Sun, Xinwen Zhang, Zongyou Xia, ZhiRong Yao
+2 more Xiaobo Feng, Jianying Liang
Cited by: 1
References: 16

Abstract

Chronic granulomatous dermatitis in children with inborn errors of immunity poses diagnostic challenges, particularly when persistent viral detection coexists with impaired T-cell surveillance. We report two children with 22q11.2 deletion syndrome who developed chronic facial granulomatous dermatitis in the setting of T-cell immunodeficiency and EBV detection. Both patients had persistent facial plaques refractory to conventional antimicrobial or anti-inflammatory treatment, elevated EBV DNA in blood and granulomatous lymphohistiocytic infiltrates on skin biopsy. Tissue mNGS identified EBV in lesional specimens. In patient 1, EBER positivity and a restricted/skewed TRB repertoire provided stronger support for local EBV-associated immune dysregulation. In patient 2, EBV was detected by mNGS, but EBER staining was negative, additional microorganisms were identified, and TRB findings were more consistent with reactive or oligoclonal expansion, making causal attribution less certain. Rubella virus-associated granuloma, a key differential diagnosis in immunodeficient children, was not supported by lesion-directed testing. These cases highlight chronic granulomatous dermatitis as a possible manifestation of virus-associated immune dysregulation in DiGeorge syndrome and emphasize that mNGS results require careful integration with tissue localization, histopathology, clonality assessment, and immune context.

Fields of Study & Subjects

Immunodeficiency and Autoimmune Disorders Skin Diseases and Diabetes Congenital heart defects research

Publication details

Journal / source
International Journal of Infectious Diseases
Publisher
Elsevier BV
Volume
169
Pages
108776–108776
Publication date
9 May 2026
Language
EN