Clinical phenotypes in α 1 -antitrypsin deficiency: a cluster analysis on EARCO data

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Authors: Anse Somers, Kenneth Verstraete, Ella Demesmaeker, María Torres-Duran, Alice M. Turner, Hanan A. Tanash, Carlota Rodríguez‐García, Jens‐Ulrik Stæhr Jensen, Angelo Guido Corsico, José Luís López-Campos, Kenneth R. Chapman, Christian Friedrich Clarenbach
+88 more Catarina Guimarães, Eva Bartošovská, José María Hernández Pérez, Juan Luis Rodríguez Hermosa, Beatriz Lara, Marc Miravitlles, Wim Janssens, Stephanie Everaerts, EARCO study investigators, Mariano Fernández Acquier, Andrés L. Echazarreta5, Georg‐Christian Funk, Karin Schmid-Scherzer, Wim Janssens, Silvia Pérez-Bogerd, Kenneth R. Chapman, Leidy Prada, Ana Hečimović, Eva Bartošovská, Alan Altraja, Jaanus Martti, Eric Y.E. Derom, M. Zysman, Jean-François Mornex, Martine Reynaud‐Gaubert, Timm Greulich, Felix J.F. Herth, Franziska Trudzinski, Rembert Koczulla, Matthias Welsner, Gerry McElvaney, Angelo Guido Corsico, Ilaria Ferrarotti, Simone Scarlata, Mario Malerba, Luciano Corda, Jan Stolk, Emily F.A. van ’t Wout, Joanna Chorowstoska-Wyminko, Catarina Guimaraes, Maria Sucena, Ana Caldas, Raquel Marçôa, Isabel Ruivo dos Santos, Bebiana Conde, Maria Joana Reis Amado, Maia Da Silva, Rita Boaventura, Cristina Santos, Gabriela Santos, Filipa Costa, Teresa Martín, Joana Gomes, Sónia Isabel Silva Guerra, Ruxandra Ulmeanu, María Torres-Duran, Marc Miravitlles, Míriam Barrecheguren, Juan Luis Rodríguez Hermosa, Myriam Calle, José María Hernández Pérez, José Luís López-Campos, Francisco Casas Maldonado, Ana Bustamante, Carlota Rodríguez‐García, Marta María García Clemente, Cruz González, Eva María Tabernero, Lourdes Lázaro, Virginia Almadana, Mar Fernández‐Nieto, Francisco Javier Michel de la Rosa, Carlos Martínez‐Rivera, Layla Diab, María Isabel Parra, Nuria Rodriguez-Lázaro, Susana Martínez, Rosanel Amaro, Ramón Antonio Tubío-Pérez, Hanan A. Tanash, Eeva Piitulainen, Christian F. Clarenbach, Serap Argun Barış, Dilek Karadoğan, Sebahat Genç, Ouksel Hakima, Alice M. Turner, Beatriz Lara
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References: 38

Abstract

Background: α-1 antitrypsin deficiency (AATD) is a rare, monogenic disorder predisposing individuals to liver and lung diseases. Yet, even within the same genotype, AATD is very heterogeneous in clinical presentation. This heterogeneity suggests a complex interplay of environmental and (epi)genetic factors, highlighting the need for a detection and study of clinical phenotypes. Methods: Here, we performed a cluster analysis using baseline data from the European Alpha-1 Research Collaboration (EARCO) to identify distinct clinical phenotypes in AATD. Results: We identified six clusters of AATD clinical phenotypes using K-prototypes with a cross-validated weighted F1 score of 0.926. Moreover, using a trained random forest classifier, we identified age at diagnosis, lung function and tobacco consumption as the most important features in distinguishing these clusters, in addition to the AATD-associated genotype. Conclusions: Overall, these findings underscore the fact that, beyond genotype, a multitude of other factors significantly influence AATD clinical phenotypes. Accordingly, this emphasises the importance of integrating (epi)genetic, environmental and behavioural data in future fundamental and translational research to unravel the complex mechanisms underlying patient heterogeneity. Moreover, longitudinal follow-up of individuals allocated to these clusters will help to better understand disease progression and to assess the potential benefits of specific therapies in different phenotypes.

Fields of Study & Subjects

Chronic Obstructive Pulmonary Disease (COPD) Research Protease and Inhibitor Mechanisms Cystic Fibrosis Research Advances

Publication details

Journal / source
ERJ Open Research
Volume
12
Issue
4
Pages
01597–2025
Publication date
6 March 2026
Language
EN